Trial Outcomes & Findings for Pharmacokinetic Study of Deferiprone in Paediatric Patients (NCT NCT01740713)

NCT ID: NCT01740713

Last Updated: 2017-01-11

Results Overview

Plasma clearance after oral administration. The parameter was estimated through a population pharmacokinetic model, during which concentration data obtained after single oral dose ( at 3 dose levels) of DFP in patients aged from 1 month to less than 6 years of age.

Recruitment status

COMPLETED

Study phase

PHASE2

Target enrollment

23 participants

Primary outcome timeframe

Day 1 of single dose treatment (6 sampling time range: from predose up to 8h post first administration)

Results posted on

2017-01-11

Participant Flow

A total of 23 children affected by transfusion-dependent haemoglobinopathies were enrolled in this study. Of these 23 children, 2 were screening failures and 3 early terminations.

Participant milestones

Participant milestones
Measure
Deferiprone 25 mg/kg/Day
Deferiprone will be administered at 25 mg/kg/day Deferiprone, dose level 1: deferiprone liquid oral solution (80 mg/ml)
Deferiprone 50 mg/kg/da
Deferiprone will be administered at 50 mg/kg/day Deferiprone, dose level 2: deferiprone liquid oral solution (80 mg/ml)
Deferiprone 100 mg/kg/Day
Deferiprone will be administered at 100 mg/kg/day Deferiprone, dose level 3: deferiprone liquid oral solution (80 mg/ml)
Overall Study
STARTED
6
8
7
Overall Study
COMPLETED
6
6
6
Overall Study
NOT COMPLETED
0
2
1

Reasons for withdrawal

Withdrawal data not reported

Baseline Characteristics

Pharmacokinetic Study of Deferiprone in Paediatric Patients

Baseline characteristics by cohort

Baseline characteristics by cohort
Measure
Deferiprone 25 mg/kg/Day
n=6 Participants
Deferiprone will be administered at 25 mg/kg/day Deferiprone, dose level 1: deferiprone liquid oral solution (80 mg/ml)
Deferiprone 50 mg/kg/Day
n=8 Participants
Deferiprone will be administered at 50 mg/kg/day Deferiprone, dose level 2: deferiprone liquid oral solution (80 mg/ml)
Deferiprone 100 mg/kg/Day
n=7 Participants
Deferiprone will be administered at 100 mg/kg/day Deferiprone, dose level 3: deferiprone liquid oral solution (80 mg/ml)
Total
n=21 Participants
Total of all reporting groups
Age, Categorical
<=18 years
6 Participants
n=99 Participants
8 Participants
n=107 Participants
7 Participants
n=206 Participants
21 Participants
n=7 Participants
Age, Categorical
Between 18 and 65 years
0 Participants
n=99 Participants
0 Participants
n=107 Participants
0 Participants
n=206 Participants
0 Participants
n=7 Participants
Age, Categorical
>=65 years
0 Participants
n=99 Participants
0 Participants
n=107 Participants
0 Participants
n=206 Participants
0 Participants
n=7 Participants
Gender
Female
3 Participants
n=99 Participants
4 Participants
n=107 Participants
4 Participants
n=206 Participants
11 Participants
n=7 Participants
Gender
Male
3 Participants
n=99 Participants
4 Participants
n=107 Participants
3 Participants
n=206 Participants
10 Participants
n=7 Participants
Region of Enrollment
Italy
6 participants
n=99 Participants
8 participants
n=107 Participants
7 participants
n=206 Participants
21 participants
n=7 Participants

PRIMARY outcome

Timeframe: Day 1 of single dose treatment (6 sampling time range: from predose up to 8h post first administration)

Plasma clearance after oral administration. The parameter was estimated through a population pharmacokinetic model, during which concentration data obtained after single oral dose ( at 3 dose levels) of DFP in patients aged from 1 month to less than 6 years of age.

Outcome measures

Outcome measures
Measure
PK Population
n=18 Participants
Deferiprone liquid oral solution (80 mg/ml) has been administered at 25/50/100 mg/kg/day
Deferiprone 50 mg/kg/Day
Deferiprone will be administered at 50 mg/kg/day Deferiprone, dose level 2: deferiprone liquid oral solution (80 mg/ml)
Deferiprone 100 mg/kg/Day
Deferiprone will be administered at 100 mg/kg/day Deferiprone, dose level 3: deferiprone liquid oral solution (80 mg/ml)
CL/F
8.3 litre/h
Standard Error 0.569

PRIMARY outcome

Timeframe: Day 1 of single dose treatment (6 sampling time range: from predose up to 8h post first administration)

Area under concentration versus time curve from 0 to 8 h post dosing. Secondary pharmacokinetic parameter derived on the basis of the individual predicted concentration vs. time profiles, through the pop-PK model.

Outcome measures

Outcome measures
Measure
PK Population
n=6 Participants
Deferiprone liquid oral solution (80 mg/ml) has been administered at 25/50/100 mg/kg/day
Deferiprone 50 mg/kg/Day
n=6 Participants
Deferiprone will be administered at 50 mg/kg/day Deferiprone, dose level 2: deferiprone liquid oral solution (80 mg/ml)
Deferiprone 100 mg/kg/Day
n=6 Participants
Deferiprone will be administered at 100 mg/kg/day Deferiprone, dose level 3: deferiprone liquid oral solution (80 mg/ml)
AUC (0-8h)
116.7 micromol*h/L
Interval 90.6 to 129.0
210.0 micromol*h/L
Interval 173.1 to 266.6
428.8 micromol*h/L
Interval 291.4 to 547.8

PRIMARY outcome

Timeframe: Day 1 of single dose treatment (6 sampling time range: from predose up to 8h post first administration)

volume of distribution after oral administration. The parameter was estimated through a population pharmacokinetic model, during which concentration data obtained after single oral dose ( at 3 dose levels) of DFP in patients aged from 1 month to less than 6 years of age

Outcome measures

Outcome measures
Measure
PK Population
n=18 Participants
Deferiprone liquid oral solution (80 mg/ml) has been administered at 25/50/100 mg/kg/day
Deferiprone 50 mg/kg/Day
Deferiprone will be administered at 50 mg/kg/day Deferiprone, dose level 2: deferiprone liquid oral solution (80 mg/ml)
Deferiprone 100 mg/kg/Day
Deferiprone will be administered at 100 mg/kg/day Deferiprone, dose level 3: deferiprone liquid oral solution (80 mg/ml)
V/F
18.7 litres
Standard Error 1.16

PRIMARY outcome

Timeframe: Day 1 of single dose treatment (6 sampling time range: from predose up to 8h post first administration)

Time at which the maximum concentration (Cmax) is reached. Secondary pharmacokinetic parameters such as Cmax, Min, Tmax, Css and AUC (0-8h) were derived based on the individual predicted concentration vs. time profiles.

Outcome measures

Outcome measures
Measure
PK Population
n=6 Participants
Deferiprone liquid oral solution (80 mg/ml) has been administered at 25/50/100 mg/kg/day
Deferiprone 50 mg/kg/Day
n=6 Participants
Deferiprone will be administered at 50 mg/kg/day Deferiprone, dose level 2: deferiprone liquid oral solution (80 mg/ml)
Deferiprone 100 mg/kg/Day
n=6 Participants
Deferiprone will be administered at 100 mg/kg/day Deferiprone, dose level 3: deferiprone liquid oral solution (80 mg/ml)
Tmax
0.33 hour
Interval 0.19 to 0.92
0.33 hour
Interval 0.21 to 0.63
0.37 hour
Interval 0.27 to 0.42

PRIMARY outcome

Timeframe: Day 1 of single dose treatment (6 sampling time range: from predose up to 8h post first administration)

Absorption rate constant. The parameter was estimated through a population pharmacokinetic model, during which concentration data obtained after single oral dose ( at 3 dose levels) of DFP in patients aged from 1 month to less than 6 years of age.

Outcome measures

Outcome measures
Measure
PK Population
n=18 Participants
Deferiprone liquid oral solution (80 mg/ml) has been administered at 25/50/100 mg/kg/day
Deferiprone 50 mg/kg/Day
Deferiprone will be administered at 50 mg/kg/day Deferiprone, dose level 2: deferiprone liquid oral solution (80 mg/ml)
Deferiprone 100 mg/kg/Day
Deferiprone will be administered at 100 mg/kg/day Deferiprone, dose level 3: deferiprone liquid oral solution (80 mg/ml)
Ka
9.13 h^-1
Standard Error 1.41

PRIMARY outcome

Timeframe: Day 1 of single dose treatment (6 sampling time range: from predose up to 8h post first administration)

Maximum concentration reached in plasma. Secondary pharmacokinetic parameter derived on the basis of the individual predicted concentration vs. time profiles, through the pop-PK model.

Outcome measures

Outcome measures
Measure
PK Population
n=6 Participants
Deferiprone liquid oral solution (80 mg/ml) has been administered at 25/50/100 mg/kg/day
Deferiprone 50 mg/kg/Day
n=6 Participants
Deferiprone will be administered at 50 mg/kg/day Deferiprone, dose level 2: deferiprone liquid oral solution (80 mg/ml)
Deferiprone 100 mg/kg/Day
n=6 Participants
Deferiprone will be administered at 100 mg/kg/day Deferiprone, dose level 3: deferiprone liquid oral solution (80 mg/ml)
Cmax
61.7 microM
Interval 45.1 to 80.7
119.8 microM
Interval 106.0 to 154.0
229.5 microM
Interval 179.7 to 278.1

PRIMARY outcome

Timeframe: Day 1 of single dose treatment (6 sampling time range: from predose up to 8h post first administration)

Plasma concentration reached at steady state. Secondary pharmacokinetic parameter derived on the basis of the individual predicted concentration vs. time profiles, through the pop-PK model.

Outcome measures

Outcome measures
Measure
PK Population
n=6 Participants
Deferiprone liquid oral solution (80 mg/ml) has been administered at 25/50/100 mg/kg/day
Deferiprone 50 mg/kg/Day
n=6 Participants
Deferiprone will be administered at 50 mg/kg/day Deferiprone, dose level 2: deferiprone liquid oral solution (80 mg/ml)
Deferiprone 100 mg/kg/Day
n=6 Participants
Deferiprone will be administered at 100 mg/kg/day Deferiprone, dose level 3: deferiprone liquid oral solution (80 mg/ml)
Css
2.1 microM
Interval 1.6 to 2.3
3.7 microM
Interval 3.1 to 4.9
7.7 microM
Interval 5.1 to 10.0

PRIMARY outcome

Timeframe: Day 1 of single dose treatment (6 sampling time range: from predose up to 8h post first administration)

Minimum plasma concentration. Secondary pharmacokinetic parameter derived on the basis of the individual predicted concentration vs. time profiles, through the pop-PK model.

Outcome measures

Outcome measures
Measure
PK Population
n=6 Participants
Deferiprone liquid oral solution (80 mg/ml) has been administered at 25/50/100 mg/kg/day
Deferiprone 50 mg/kg/Day
n=6 Participants
Deferiprone will be administered at 50 mg/kg/day Deferiprone, dose level 2: deferiprone liquid oral solution (80 mg/ml)
Deferiprone 100 mg/kg/Day
n=6 Participants
Deferiprone will be administered at 100 mg/kg/day Deferiprone, dose level 3: deferiprone liquid oral solution (80 mg/ml)
Cmin
1.5 microM
Interval 0.92 to 2.6
1.9 microM
Interval 0.79 to 5.5
6.8 microM
Interval 3.1 to 13.9

SECONDARY outcome

Timeframe: from drug administration up to 8 days post treatment

All the medical occurrences that started after the administration of the drug

Outcome measures

Outcome measures
Measure
PK Population
n=21 Participants
Deferiprone liquid oral solution (80 mg/ml) has been administered at 25/50/100 mg/kg/day
Deferiprone 50 mg/kg/Day
Deferiprone will be administered at 50 mg/kg/day Deferiprone, dose level 2: deferiprone liquid oral solution (80 mg/ml)
Deferiprone 100 mg/kg/Day
Deferiprone will be administered at 100 mg/kg/day Deferiprone, dose level 3: deferiprone liquid oral solution (80 mg/ml)
Adverse Events
3 participants

Adverse Events

Deferiprone 25mg/kg/Day

Serious events: 0 serious events
Other events: 1 other events
Deaths: 0 deaths

Deferiprone 50 mg/kg/Day

Serious events: 0 serious events
Other events: 0 other events
Deaths: 0 deaths

Deferiprone 100 mg/kg/Day

Serious events: 0 serious events
Other events: 2 other events
Deaths: 0 deaths

Serious adverse events

Adverse event data not reported

Other adverse events

Other adverse events
Measure
Deferiprone 25mg/kg/Day
n=6 participants at risk
Deferiprone will be administered at 25 mg/kg/day Deferiprone, dose level 1: deferiprone liquid oral solution (80 mg/ml)
Deferiprone 50 mg/kg/Day
n=8 participants at risk
Deferiprone will be administered at 50 mg/kg/day Deferiprone, dose level 2: deferiprone liquid oral solution (80 mg/ml)
Deferiprone 100 mg/kg/Day
n=7 participants at risk
Deferiprone will be administered at 100 mg/kg/day Deferiprone, dose level 3: deferiprone liquid oral solution (80 mg/ml)
Pregnancy, puerperium and perinatal conditions
Infantile spitting up
0.00%
0/6 • All the medical occurrences that started after the administration of the drug under investigation have been recorded as AEs till the follow -up visit at 8 days post dosing.
0.00%
0/8 • All the medical occurrences that started after the administration of the drug under investigation have been recorded as AEs till the follow -up visit at 8 days post dosing.
28.6%
2/7 • Number of events 2 • All the medical occurrences that started after the administration of the drug under investigation have been recorded as AEs till the follow -up visit at 8 days post dosing.
Skin and subcutaneous tissue disorders
Rash trunk
16.7%
1/6 • Number of events 1 • All the medical occurrences that started after the administration of the drug under investigation have been recorded as AEs till the follow -up visit at 8 days post dosing.
0.00%
0/8 • All the medical occurrences that started after the administration of the drug under investigation have been recorded as AEs till the follow -up visit at 8 days post dosing.
0.00%
0/7 • All the medical occurrences that started after the administration of the drug under investigation have been recorded as AEs till the follow -up visit at 8 days post dosing.

Additional Information

Clinical Research Coordinator

Consorzio per Valutazioni Biologiche e Farmacologiche

Phone: 0039 0382 25075

Results disclosure agreements

  • Principal investigator is a sponsor employee
  • Publication restrictions are in place