Trial Outcomes & Findings for Comparing Pump With Subcutaneous Injection Delivery of PTH 1-34 in the Management of Chronic Hypoparathyroidism (NCT NCT00743782)

NCT ID: NCT00743782

Last Updated: 2026-03-04

Results Overview

Mean fasting serum calcium level at the end of week 13. After 13 weeks of PTH 1-34 administration, participants were admitted for five to seven days and fasting blood sample was collected each morning (6-8 am) for three days. Mean value for the three days was calculated.

Recruitment status

COMPLETED

Study phase

PHASE2

Target enrollment

21 participants

Primary outcome timeframe

Day 1-3 of inpatient evaluation at the conclusion of 13 weeks of PTH 1-34 delivered by pump or injection

Results posted on

2026-03-04

Participant Flow

One participant withdrew prior to randomization

Participant milestones

Participant milestones
Measure
PTH 1-34 Delivered Through Pump, Then Subcutaneous Injection
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours, followed by PTH 1-34 twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
PTH 1-34 Subcutaneous Injection, Then Delivered Through Pump
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks, followed by PTH 1-34 titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
Period 1
STARTED
10
10
Period 1
COMPLETED
10
10
Period 1
NOT COMPLETED
0
0
Period 2
STARTED
10
10
Period 2
COMPLETED
10
10
Period 2
NOT COMPLETED
0
0

Reasons for withdrawal

Withdrawal data not reported

Baseline Characteristics

Comparing Pump With Subcutaneous Injection Delivery of PTH 1-34 in the Management of Chronic Hypoparathyroidism

Baseline characteristics by cohort

Baseline characteristics by cohort
Measure
Overall Study Participants
n=20 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years were randomized to receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) either as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults, with pods containing drug changed every 72 hours, or PTH 1-34 twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks followed by subsequent intervention for 13 weeks.
Age, Customized
7-20 years
12 Participants
n=41 Participants
Age, Customized
>= 21 years
8 Participants
n=41 Participants
Sex: Female, Male
Female
14 Participants
n=41 Participants
Sex: Female, Male
Male
6 Participants
n=41 Participants
Ethnicity (NIH/OMB)
Hispanic or Latino
4 Participants
n=41 Participants
Ethnicity (NIH/OMB)
Not Hispanic or Latino
16 Participants
n=41 Participants
Ethnicity (NIH/OMB)
Unknown or Not Reported
0 Participants
n=41 Participants
Race (NIH/OMB)
American Indian or Alaska Native
0 Participants
n=41 Participants
Race (NIH/OMB)
Asian
1 Participants
n=41 Participants
Race (NIH/OMB)
Native Hawaiian or Other Pacific Islander
0 Participants
n=41 Participants
Race (NIH/OMB)
Black or African American
0 Participants
n=41 Participants
Race (NIH/OMB)
White
16 Participants
n=41 Participants
Race (NIH/OMB)
More than one race
2 Participants
n=41 Participants
Race (NIH/OMB)
Unknown or Not Reported
1 Participants
n=41 Participants
Region of Enrollment
United States
20 participants
n=41 Participants

PRIMARY outcome

Timeframe: Day 1-3 of inpatient evaluation at the conclusion of 13 weeks of PTH 1-34 delivered by pump or injection

Population: Intent-to-treat (ITT) population

Mean fasting serum calcium level at the end of week 13. After 13 weeks of PTH 1-34 administration, participants were admitted for five to seven days and fasting blood sample was collected each morning (6-8 am) for three days. Mean value for the three days was calculated.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=12 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
n=12 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Serum Calcium in Children and Young Adults
2.02 mmol/liter
Standard Error 0.053
1.88 mmol/liter
Standard Error 0.03

PRIMARY outcome

Timeframe: Day 1-3 of inpatient evaluation at the conclusion of 13 weeks of PTH 1-34 delivered by pump or injection

Population: Intent-to-treat (ITT) population

Mean fasting serum calcium level at the end of week 13. After 13 weeks of PTH 1-34 administration, participants were admitted for five to seven days and fasting blood sample was collected each morning (6-8 am) for three days. Mean value for the three days was calculated.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=8 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
n=8 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Serum Calcium in Adults
2.078 mmol/liter
Standard Error 0.065
2.153 mmol/liter
Standard Error 0.042

PRIMARY outcome

Timeframe: Day 1-3 of inpatient evaluation at the conclusion of 13 weeks of PTH 1-34 delivered by pump or injection

Population: Intent-to-treat (ITT) population

Mean 24-hour urine calcium excretion at the end of week 13. After 13 weeks of PTH 1-34 administration, participants were admitted for five to seven days and 24 hour urine sample was collected each day for three days. Mean value for the three days was calculated with values corrected for body surface area in children and young adults.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=12 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
n=12 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Urine Calcium Excretion in Children and Young Adults
5.17 mmol/24h
Standard Error 1.10
6.67 mmol/24h
Standard Error 0.76

PRIMARY outcome

Timeframe: Day 1-3 of inpatient evaluation at the conclusion of 13 weeks of PTH 1-34 delivered by pump or injection

Population: Intent-to-treat (ITT) population

Mean 24-hour urine calcium excretion at the end of week 13. After 13 weeks of PTH 1-34 administration, participants were admitted for five to seven days and 24 hour urine sample was collected each day for three days. Mean value for the three days was calculated.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=8 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
n=8 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Urine Calcium Excretion in Adults
3.981 mmol/24h
Standard Error 0.679
9.655 mmol/24h
Standard Error 1.045

SECONDARY outcome

Timeframe: Day 1-3 of inpatient evaluation at the conclusion of 13 weeks of PTH 1-34 delivered by pump or injection

Population: Intent-to-treat (ITT) population

Mean fasting serum phosphorus level at the end of week 13. After 13 weeks of PTH 1-34 administration, participants were admitted for five to seven days and fasting blood sample was collected each morning (6-8 am) for three days. Mean value for the three days was calculated.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=12 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
n=12 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Serum Phosphorus in Children and Young Adults
1.78 mmol/liter
Standard Error 0.07
1.58 mmol/liter
Standard Error 0.07

SECONDARY outcome

Timeframe: Day 1-3 of inpatient evaluation at the conclusion of 13 weeks of PTH 1-34 delivered by pump or injection

Population: Intent-to-treat (ITT) population

Mean fasting serum phosphorus level at the end of week 13. After 13 weeks of PTH 1-34 administration, participants were admitted for five to seven days and fasting blood sample was collected each morning (6-8 am) for three days. Mean value for the three days was calculated.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=8 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
n=8 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Serum Phosphorus in Adults
1.401 mmol/liter
Standard Error 0.086
1.350 mmol/liter
Standard Error 0.050

SECONDARY outcome

Timeframe: Day 1-3 of inpatient evaluation at the conclusion of 13 weeks of PTH 1-34 delivered by pump or injection

Population: Intent-to-treat (ITT) population

Mean 24-hour urine phosphorus excretion at the end of week 13. After 13 weeks of PTH 1-34 administration, participants were admitted for five to seven days and 24 hour urine sample was collected each day for three days. Mean value for the three days was calculated with values corrected for body surface area in children and young adults.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=12 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
n=12 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Urine Phosphorus Excretion in Children and Young Adults
1.10 mmol/24h
Standard Error 0.25
0.83 mmol/24h
Standard Error 0.10

SECONDARY outcome

Timeframe: Day 1-3 of inpatient evaluation at the conclusion of 13 weeks of PTH 1-34 delivered by pump or injection

Population: Intent-to-treat (ITT) population

Mean 24-hour urine phosphorus excretion at the end of week 13. After 13 weeks of PTH 1-34 administration, participants were admitted for five to seven days and 24 hour urine sample was collected each day for three days. Mean value for the three days was calculated.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=8 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
n=8 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Urine Phosphorus Excretion in Adults
28.697 mmol/24h
Standard Error 3.023
31.792 mmol/24h
Standard Error 3.723

SECONDARY outcome

Timeframe: Day 1-3 of inpatient evaluation at the conclusion of 13 weeks of PTH 1-34 delivered by pump or injection

Population: Intent-to-treat (ITT) population

Mean fasting serum magnesium level at the end of week 13. After 13 weeks of PTH 1-34 administration, participants were admitted for five to seven days and fasting blood sample was collected each morning (6-8 am) for three days. Mean value for the three days was calculated.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=12 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
n=12 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Serum Magnesium in Children and Young Adults
0.74 mmol/liter
Standard Error 0.02
0.65 mmol/liter
Standard Error 0.02

SECONDARY outcome

Timeframe: Day 1-3 of inpatient evaluation at the conclusion of 13 weeks of PTH 1-34 delivered by pump or injection

Population: Intent-to-treat (ITT) population

Mean fasting serum magnesium level at the end of week 13. After 13 weeks of PTH 1-34 administration, participants were admitted for five to seven days and fasting blood sample was collected each morning (6-8 am) for three days. Mean value for the three days was calculated.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=8 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
n=8 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Serum Magnesium in Adults
0.855 mmol/liter
Standard Error 0.020
0.778 mmol/liter
Standard Error 0.017

SECONDARY outcome

Timeframe: Day 1-3 of inpatient evaluation at the conclusion of 13 weeks of PTH 1-34 delivered by pump or injection

Population: Intent-to-treat (ITT) population

Mean 24-hour urine magnesium excretion at the end of week 13. After 13 weeks of PTH 1-34 administration, participants were admitted for five to seven days and 24 hour urine sample was collected each day for three days. Mean value for the three days was calculated with values corrected for body surface area in children and young adults.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=12 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
n=12 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Urine Magnesium Excretion in Children and Young Adults
6.06 mmol/24h
Standard Error 1.28
7.38 mmol/24h
Standard Error 1.33

SECONDARY outcome

Timeframe: Day 1-3 of inpatient evaluation at the conclusion of 13 weeks of PTH 1-34 delivered by pump or injection

Population: Intent-to-treat (ITT) population

Mean 24-hour urine magnesium excretion at the end of week 13. After 13 weeks of PTH 1-34 administration, participants were admitted for five to seven days and 24 hour urine sample was collected each day for three days. Mean value for the three days was calculated.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=8 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
n=8 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Urine Magnesium Excretion in Adults
4.007 mmol/24h
Standard Error 0.363
4.766 mmol/24h
Standard Error 0.748

SECONDARY outcome

Timeframe: Day 1-3 of inpatient evaluation at the conclusion of 13 weeks of PTH 1-34 delivered by pump or injection

Population: Intent-to-treat (ITT) population

Mean fasting serum alkaline phosphatase level at the end of week 13. After 13 weeks of PTH 1-34 administration, participants were admitted for five to seven days and fasting blood sample was collected each morning (6-8 am) for three days. Mean value for the three days was calculated.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=12 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
n=12 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Serum Alkaline Phosphatase in Children and Young Adults
147.93 U/liter
Standard Error 19.58
242.31 U/liter
Standard Error 44.54

SECONDARY outcome

Timeframe: Day 1-3 of inpatient evaluation at the conclusion of 13 weeks of PTH 1-34 delivered by pump or injection

Population: Intent-to-treat (ITT) population

Mean fasting serum alkaline phosphatase level at the end of week 13. After 13 weeks of PTH 1-34 administration, participants were admitted for five to seven days and fasting blood sample was collected each morning (6-8 am) for three days. Mean value for the three days was calculated.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=8 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
n=8 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Serum Alkaline Phosphatase in Adults
92.531 U/liter
Standard Error 12.242
109.191 U/liter
Standard Error 15.105

SECONDARY outcome

Timeframe: Day 1-3 of inpatient evaluation at the conclusion of 13 weeks of PTH 1-34 delivered by pump or injection

Population: Intent-to-treat (ITT) population

Mean fasting serum bone-specific alkaline phosphatase level at the end of week 13. After 13 weeks of PTH 1-34 administration, participants were admitted for five to seven days and fasting blood sample was collected each morning (6-8 am) for three days. Mean value for the three days was calculated.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=12 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
n=12 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Serum Bone-specific Alkaline Phosphatase in Children and Young Adults
51.68 MCG/L
Standard Error 8.90
81.64 MCG/L
Standard Error 16.56

SECONDARY outcome

Timeframe: Day 1-3 of inpatient evaluation at the conclusion of 13 weeks of PTH 1-34 delivered by pump or injection

Population: Intent-to-treat (ITT) population

Mean fasting serum 1,25-hydroxyvitamin D3 level at the end of week 13. After 13 weeks of PTH 1-34 administration, participants were admitted for five to seven days and fasting blood sample was collected each morning (6-8 am) for three days. Mean value for the three days was calculated.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=12 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
n=12 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Serum 1,25-hydroxyvitamin D3 in Children and Young Adults
75.21 pg/ml
Standard Error 7.78
55.63 pg/ml
Standard Error 5.07

SECONDARY outcome

Timeframe: Day 1-3 of inpatient evaluation at the conclusion of 13 weeks of PTH 1-34 delivered by pump or injection

Population: Intent-to-treat (ITT) population

Mean fasting serum 1,25-hydroxyvitamin D3 level at the end of week 13. After 13 weeks of PTH 1-34 administration, participants were admitted for five to seven days and fasting blood sample was collected each morning (6-8 am) for three days. Mean value for the three days was calculated.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=8 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
n=8 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Serum 1,25-hydroxyvitamin D3 in Adults
32 pg/ml
Standard Error 3.257
35.286 pg/ml
Standard Error 3.239

SECONDARY outcome

Timeframe: Day 1-3 of inpatient evaluation at the conclusion of 13 weeks of PTH 1-34 delivered by pump or injection

Population: Intent-to-treat (ITT) population

Mean fasting serum 25-hydroxyvitamin D3 level at the end of week 13. After 13 weeks of PTH 1-34 administration, participants were admitted for five to seven days and fasting blood sample was collected each morning (6-8 am) for three days. Mean value for the three days was calculated.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=12 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
n=12 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Serum 25-hydroxyvitamin D3 in Children and Young Adults
37.96 ng/ml
Standard Error 3.23
32.92 ng/ml
Standard Error 3.46

SECONDARY outcome

Timeframe: Day 1-3 of inpatient evaluation at the conclusion of 13 weeks of PTH 1-34 delivered by pump or injection

Population: Intent-to-treat (ITT) population

Mean fasting serum 25-hydroxyvitamin D3 level at the end of week 13. After 13 weeks of PTH 1-34 administration, participants were admitted for five to seven days and fasting blood sample was collected each morning (6-8 am) for three days. Mean value for the three days was calculated.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=8 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
n=8 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Serum 25-hydroxyvitamin D3 in Adults
34.5 ng/ml
Standard Error 2.909
32.143 ng/ml
Standard Error 3.612

SECONDARY outcome

Timeframe: Day 1-3 of inpatient evaluation at the conclusion of 13 weeks of PTH 1-34 delivered by pump or injection

Population: Intent-to-treat (ITT) population

Mean 24-hour urine creatinine clearance excretion at the end of week 13. After 13 weeks of PTH 1-34 administration, participants were admitted for five to seven days and 24 hour urine sample was collected each day for three days. Mean value for the three days was calculated with values corrected for body surface area in children and young adults.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=12 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
n=12 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Urine Creatinine Clearance Excretion in Children and Young Adults
111.57 ml/min
Standard Error 13.91
106.63 ml/min
Standard Error 6.74

SECONDARY outcome

Timeframe: Day 1-3 of inpatient evaluation at the conclusion of 13 weeks of PTH 1-34 delivered by pump or injection

Population: Intent-to-treat (ITT) population

Mean 24-hour urine creatinine clearance excretion at the end of week 13. After 13 weeks of PTH 1-34 administration, participants were admitted for five to seven days and 24 hour urine sample was collected each day for three days. Mean value for the three days was calculated.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=8 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
n=8 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Urine Creatinine Clearance Excretion in Adults
106.938 ml/min
Standard Error 9.235
114.021 ml/min
Standard Error 10.736

SECONDARY outcome

Timeframe: Day 1-3 of inpatient evaluation at the conclusion of 13 weeks of PTH 1-34 delivered by pump or injection

Population: Intent-to-treat (ITT) population

Mean fasting serum osteocalcin level at the end of week 13. After 13 weeks of PTH 1-34 administration, participants were admitted for five to seven days and fasting blood sample was collected each morning (6-8 am) for three days. Mean value for the three days was calculated.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=12 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
n=12 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Serum Osteocalcin in Children and Young Adults
188.75 ng/mL
Standard Error 20.72
308.16 ng/mL
Standard Error 43.27

SECONDARY outcome

Timeframe: Day 1-3 of inpatient evaluation at the conclusion of 13 weeks of PTH 1-34 delivered by pump or injection

Population: Intent-to-treat (ITT) population

Mean fasting serum osteocalcin level at the end of week 13. After 13 weeks of PTH 1-34 administration, participants were admitted for five to seven days and fasting blood sample was collected each morning (6-8 am) for three days. Mean value for the three days was calculated.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=8 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
n=8 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Serum Osteocalcin in Adults
40.963 ng/mL
Standard Error 9.714
73.408 ng/mL
Standard Error 16.401

SECONDARY outcome

Timeframe: Day 1-3 of inpatient evaluation at the conclusion of 13 weeks of PTH 1-34 delivered by pump or injection

Population: Intent-to-treat (ITT) population

Mean 24-hour urine N-terminal telopeptide of type 1 collagen excretion at the end of week 13. After 13 weeks of PTH 1-34 administration, participants were admitted for five to seven days and 24 hour urine sample was collected each day for three days. Mean value for the three days was calculated with values corrected for body surface area in children and young adults.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=12 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
n=12 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Urine N-terminal Telopeptide Level in Children and Young Adults
404.79 nmol/mmol
Standard Error 87.00
1116.75 nmol/mmol
Standard Error 323.91

SECONDARY outcome

Timeframe: Day 1-3 of inpatient evaluation at the conclusion of 13 weeks of PTH 1-34 delivered by pump or injection

Population: Intent-to-treat (ITT) population

Mean 24-hour urine N-terminal telopeptide of type 1 collagen excretion at the end of week 13. After 13 weeks of PTH 1-34 administration, participants were admitted for five to seven days and 24 hour urine sample was collected each day for three days. Mean value for the three days was calculated.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=8 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
n=8 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Urine N-terminal Telopeptide Level in Adults
46.625 nmol/mmol
Standard Error 8.729
116.063 nmol/mmol
Standard Error 26.567

SECONDARY outcome

Timeframe: Day 1-3 of baseline initial inpatient evaluation

Population: Intent-to-treat (ITT) population

Mean fasting serum calcium, phosphorus, and magnesium levels first three days of initial baseline inpatient admission. Participants were admitted for five to seven days and fasting blood sample was collected each morning (6-8 am) for three days. Mean value for the three days was calculated.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=20 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Blood Mineral Levels - Calcium, Phosphorus, Magnesium
Serum Magnesium (Adults)
0.842 mmol/liter
Standard Error 0.034
Mean Blood Mineral Levels - Calcium, Phosphorus, Magnesium
Serum Calcium (Children and young adults)
1.967 mmol/liter
Standard Error 0.038
Mean Blood Mineral Levels - Calcium, Phosphorus, Magnesium
Serum Calcium (Adults)
2.144 mmol/liter
Standard Error 0.059
Mean Blood Mineral Levels - Calcium, Phosphorus, Magnesium
Serum Phosphorus (Children and young adults)
1.662 mmol/liter
Standard Error 0.096
Mean Blood Mineral Levels - Calcium, Phosphorus, Magnesium
Serum Phosphorus (Adults)
1.475 mmol/liter
Standard Error 0.042
Mean Blood Mineral Levels - Calcium, Phosphorus, Magnesium
Serum Magnesium (Children and young adults)
0.700 mmol/liter
Standard Error 0.019

SECONDARY outcome

Timeframe: Day 1-3 of baseline initial inpatient evaluation

Population: Intent-to-treat (ITT) population

Mean 24-hour urine calcium, phosphorus, and magnesium excretion first 3 days of initial baseline inpatient admission. Participants were admitted for five to seven days and 24 hour urine sample was collected each day for three days. Mean value for the three days was calculated with values corrected for body surface area in children and young adults.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=20 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Urine Mineral Excretion - Calcium, Phosphorus, Magnesium
Urine calcium excretion (Children and young adults)
7.176 mmol/24h
Standard Error 0.649
Mean Urine Mineral Excretion - Calcium, Phosphorus, Magnesium
Urine calcium excretion (Adults)
9.371 mmol/24h
Standard Error 1.323
Mean Urine Mineral Excretion - Calcium, Phosphorus, Magnesium
Urine phosphorus excretion (Children and young adults)
0.747 mmol/24h
Standard Error 0.070
Mean Urine Mineral Excretion - Calcium, Phosphorus, Magnesium
Urine phosphorus excretion (Adults)
26.41 mmol/24h
Standard Error 3.982
Mean Urine Mineral Excretion - Calcium, Phosphorus, Magnesium
Urine magnesium excretion (Children and young adults)
6.975 mmol/24h
Standard Error 1.212
Mean Urine Mineral Excretion - Calcium, Phosphorus, Magnesium
Urine magnesium excretion (Adults)
5.665 mmol/24h
Standard Error 0.386

SECONDARY outcome

Timeframe: Day 1-3 of baseline initial inpatient evaluation

Population: Intent-to-treat (ITT) population

Mean fasting serum alkaline phosphatase level first 3 days of initial baseline inpatient admission. Participants were admitted for five to seven days and fasting blood sample was collected each morning (6-8 am) for three days. Mean value for the three days was calculated.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=20 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Serum Alkaline Phosphatase
Children and young adults
180.736 U/liter
Standard Error 28.050
Mean Serum Alkaline Phosphatase
Adults
60.729 U/liter
Standard Error 4.499

SECONDARY outcome

Timeframe: Day 1-3 of baseline initial inpatient evaluation

Population: Intent-to-treat (ITT) population

Mean fasting serum bone specific alkaline phosphatase level first 3 days of initial baseline inpatient admission. Participants were admitted for five to seven days and fasting blood sample was collected each morning (6-8 am) for three days. Mean value for the three days was calculated.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=12 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Serum Bone Specific Alkaline Phosphatase in Children and Young Adults
66.838 MCG/L
Standard Error 13.594

SECONDARY outcome

Timeframe: Day 1-3 of baseline initial inpatient evaluation

Population: Intent-to-treat (ITT) population

Mean fasting serum 1,25-hydroxyvitamin D3 level first 3 days of initial baseline inpatient admission. Participants were admitted for five to seven days and fasting blood sample was collected each morning (6-8 am) for three days. Mean value for the three days was calculated.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=20 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Serum 1,25-hydroxyvitamin D3
Children and young adults
56.083 pg/ml
Standard Error 6.605
Mean Serum 1,25-hydroxyvitamin D3
Adults
33.063 pg/ml
Standard Error 4.524

SECONDARY outcome

Timeframe: Day 1-3 of baseline initial inpatient evaluation

Population: Intent-to-treat (ITT) population

Mean fasting serum 25-hydroxyvitamin D3 and osteocalcin levels first 3 days of initial baseline inpatient admission. Participants were admitted for five to seven days and fasting blood sample was collected each morning (6-8 am) for three days. Mean value for the three days was calculated.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=20 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Serum Bone Minerals - 25-hydroxyvitamin D3 and Osteocalcin
Osteocalcin (Adults)
15.992 ng/ml
Standard Error 4.0746
Mean Serum Bone Minerals - 25-hydroxyvitamin D3 and Osteocalcin
25-hydroxyvitamin D3 (Children and young adults)
40.5 ng/ml
Standard Error 4.391
Mean Serum Bone Minerals - 25-hydroxyvitamin D3 and Osteocalcin
25-hydroxyvitamin D3 (Adults)
33.436 ng/ml
Standard Error 4.669
Mean Serum Bone Minerals - 25-hydroxyvitamin D3 and Osteocalcin
Osteocalcin (Children and young adults)
274.356 ng/ml
Standard Error 50.009

SECONDARY outcome

Timeframe: Day 1-3 of baseline initial inpatient evaluation

Population: Intent-to-treat (ITT) population

Mean 24-hour urine creatinine clearance excretion first 3 days of initial baseline inpatient admission. Participants were admitted for five to seven days and 24 hour urine sample was collected each day for three days. Mean value for the three days was calculated with values corrected for body surface area in children.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=20 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Urine Creatinine Clearance Excretion
Children and young adults
99.100 ml/min
Standard Error 10.760
Mean Urine Creatinine Clearance Excretion
Adults
109.625 ml/min
Standard Error 9.956

SECONDARY outcome

Timeframe: Day 1-3 of baseline initial inpatient evaluation

Population: Intent-to-treat (ITT) population

Mean 24-hour urine N-terminal telopeptide of type 1 collagen excretion first 3 days of initial baseline inpatient admission. Participants were admitted for five to seven days and 24 hour urine sample was collected each day for three days. Mean value for the three days was calculated with values corrected for body surface area in children.

Outcome measures

Outcome measures
Measure
PTH 1-34 Delivered Through Pump
n=20 Participants
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) as titrated infusion through an insulin pump based on body weight, at 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, receive synthetic human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
Mean Urine N-terminal Telopeptide Level
Children and young adults
520.830 NMOL/MMOL
Standard Error 109.473
Mean Urine N-terminal Telopeptide Level
Adults
16.976 NMOL/MMOL
Standard Error 3.006

Adverse Events

PTH 1-34 Delivered Through Pump

Serious events: 0 serious events
Other events: 3 other events
Deaths: 0 deaths

PTH 1-34 Subcutaneous Injection

Serious events: 0 serious events
Other events: 4 other events
Deaths: 0 deaths

Serious adverse events

Adverse event data not reported

Other adverse events

Other adverse events
Measure
PTH 1-34 Delivered Through Pump
n=20 participants at risk
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, received Synthetic Human Parathyroid Hormone 1-34 (PTH 1-34) as a titrated infusion through an insulin pump based on body weight, at a mean rate of 0.32 mcg/kg/day for children and 0.17 mcg/kg/day for adults for 13 weeks, with pods containing drug changed every 72 hours.
PTH 1-34 Subcutaneous Injection
n=20 participants at risk
Children and young adults with genetic forms of hypoparathyroidism and adults with postsurgical hypoparathyroidism, ages 7 to 70 years, received Synthetic Human Parathyroid Hormone 1-34 (PTH 1-34) twice daily subcutaneous injection based on body weight, at a mean daily dose of 0.85 mcg/kg/day for children and 0.47 mcg/kg/day for adults for 13 weeks.
General disorders
Catheter site extravasation
0.00%
0/20 • 28 weeks
5.0%
1/20 • 28 weeks
General disorders
Fatigue
0.00%
0/20 • 28 weeks
5.0%
1/20 • 28 weeks
General disorders
Hyperthermia
0.00%
0/20 • 28 weeks
5.0%
1/20 • 28 weeks
General disorders
Injection site erythema
0.00%
0/20 • 28 weeks
10.0%
2/20 • 28 weeks
Infections and infestations
Pneumonia viral
0.00%
0/20 • 28 weeks
5.0%
1/20 • 28 weeks
Injury, poisoning and procedural complications
Unintentional medical device removal
15.0%
3/20 • 28 weeks
0.00%
0/20 • 28 weeks
Respiratory, thoracic and mediastinal disorders
Cough
0.00%
0/20 • 28 weeks
5.0%
1/20 • 28 weeks
Surgical and medical procedures
Hospitalisation
0.00%
0/20 • 28 weeks
5.0%
1/20 • 28 weeks

Additional Information

Dr. Karen Winer, MD

National Institute of Child Health and Human Development

Phone: +1 301 435 6877

Results disclosure agreements

  • Principal investigator is a sponsor employee
  • Publication restrictions are in place